MODERN APPROACHES TO DIAGNOSTICS AND TREATMENT OF OPTIC NEUROPATHY

Аннотация

Leber optic neuropathy is a genetic disease that causes progressive atrophy of the optic nerve and loss of vision. The pathology occurs when a mutation in mitochondrial DNA occurs, which is transmitted to children through the maternal line. The main symptom of the disease is a sharp decrease in visual acuity from normal to light perception, which most often occurs between the ages of 18 and 30. For diagnosis, ophthalmoscopy, OCT, and visual potential tests are prescribed. The diagnosis can be confirmed using molecular genetic testing. Treatment of Leber neuropathy includes neurometabolic drugs and long-term rehabilitation.

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Jalalova, D., & Kasimov, T. (2025). MODERN APPROACHES TO DIAGNOSTICS AND TREATMENT OF OPTIC NEUROPATHY. Современная наука и исследования, 4(3), 323–329. извлечено от https://www.inlibrary.uz/index.php/science-research/article/view/73511
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Аннотация

Leber optic neuropathy is a genetic disease that causes progressive atrophy of the optic nerve and loss of vision. The pathology occurs when a mutation in mitochondrial DNA occurs, which is transmitted to children through the maternal line. The main symptom of the disease is a sharp decrease in visual acuity from normal to light perception, which most often occurs between the ages of 18 and 30. For diagnosis, ophthalmoscopy, OCT, and visual potential tests are prescribed. The diagnosis can be confirmed using molecular genetic testing. Treatment of Leber neuropathy includes neurometabolic drugs and long-term rehabilitation.


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MODERN APPROACHES TO DIAGNOSTICS AND TREATMENT OF OPTIC

NEUROPATHY

Jalalova Dilfuza Zuhridinovna

Scientific supervisor.

Department of Ophthalmology, Samarkand State Medical University

Kasimov Turdali

Samarkand State Medical University, Department of Ophthalmology, 1st year clinical ordinator

https://doi.org/10.5281/zenodo.15072881

Abstract. Leber optic neuropathy is a genetic disease that causes progressive atrophy of

the optic nerve and loss of vision. The pathology occurs when a mutation in mitochondrial DNA

occurs, which is transmitted to children through the maternal line. The main symptom of the

disease is a sharp decrease in visual acuity from normal to light perception, which most often

occurs between the ages of 18 and 30. For diagnosis, ophthalmoscopy, OCT, and visual potential

tests are prescribed. The diagnosis can be confirmed using molecular genetic testing. Treatment

of Leber neuropathy includes neurometabolic drugs and long-term rehabilitation.

Keywords: Causes, Pathogenesis, Symptoms, Complications, Diagnostics, Treatment of

Leber's optic neuropathy, Conservative therapy, Experimental treatment, Rehabilitation,

Prognosis and prevention.

Introduction:

The disease is named after the German ophthalmologist Theodor Leber,

who first described 15 cases of sudden vision loss in patients from four families. The molecular

genetic basis of the disease was established in 1988 by the American biochemist D. Wallace.

Leber's hereditary optic neuropathy (LHON) occurs with a frequency of 1 case per 50

thousand people, but every ten thousandth person on the planet is a carrier of the mutation. In

Russia, the disease is more common among the population of Siberia. Men suffer from optic

neuropathy 5 times more often than women.

The disease develops as a result of mutations in mitochondrial DNA, which lead to a

disruption of the energy supply of the optic nerves and lead to their death. Up to 95% of cases are

associated with 3 types of hereditary anomalies: 3460G>A in the ND1 gene, 11778GC (ND6). The

mutation of the ND4 gene is the most common in clinical practice. Leber optic neuropathy can

also be caused by other variants of anomalies that are not well understood due to their rarity.


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Mitochondrial DNA mutations are characterized by complete penetrance, so some people

with an abnormal gene develop a pronounced clinical picture, while others remain asymptomatic

carriers throughout their lives. External triggers play a role in the development of the disease.

The most important of them are:

When the nucleotide sequence in mitochondrial DNA is disrupted, the structure of the

proteins encoded by these genes changes. Since Leber's optic neuropathy affects the ND genes

encoding proteins of complex I (NADH-ubiquinone reductase), the pathology occurs at the stage

of formation of ATP molecules. The cells of the nervous system are sensitive to the lack of energy

molecules, which leads to damage to the optic nerve.

The molecular basis of the disease is a decrease in ATP transport to the distal parts of the

axons, which leads to the initiation of apoptosis processes from the periphery. ATP deficiency is

most pronounced in the thin unmyelinated fibers that make up the optic nerve, therefore vision is

primarily affected in Leber's neuropathy. The development of pathology is facilitated by the

congenital multiplicity of axons in the optic nerve head and the special structure of the cribriform

plate.

Research methods and materials:

Leber's optic neuropathy is characterized by 3

successive stages: preclinical, acute, chronic (atrophic). The first stage is asymptomatic, but when

the patient is examined by an ophthalmologist for another reason, swelling of the optic nerve and

the appearance of telangiectasias in it are detected. The duration of this stage is not regulated, since

the disease is detected very rarely in the preclinical stage.

The acute stage of Leber's optic neuropathy most often occurs in young men aged 18 to 30

years. Patients complain of a sharp decrease in vision, similar to a central scotoma. Within 1-1.5

months, a person loses the ability to distinguish small objects, sometimes even counting fingers

up to a hundred, and only the sensation of light remains. Pathology affects both eyes

simultaneously or sequentially with an interval of 6-8 weeks.

After 6 months, the disease becomes chronic, when visual acuity is reduced to several

thousandths. During this period, nerve atrophy continues, after which the function of the eyeball

cannot be restored. The ophthalmological picture is characterized by pallor of the optic disc.

However, there are cases of reverse development of symptoms, when after some time patients

partially restore vision.

Extraocular manifestations are possible with optic neuropathy. Nerve damage can affect

more than just the optic tract, so some patients experience peripheral neuropathy, myopathy, and

muscular dystonia. If the disease manifests itself in early childhood, there is a risk of developing


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subacute necrotizing encephalomyopathy (Leigh syndrome). Sometimes, symptoms of NONLS

and MELAS syndrome overlap.

The main problem of Leber's neuropathy is loss of vision, which is especially difficult for

young patients. Against the background of blindness, severe depression develops, which can end

in suicide attempts. Since even partial restoration of vision does not occur in everyone, in the future

patients become disabled and are forced to undergo rehabilitation to adapt to new living conditions.

In some women, Leber's neuropathy occurs in the form of multiple sclerosis, with

alternating periods of exacerbation and remission. In such patients, vision loss alternates with

episodes of incomplete recovery of vision. It is characterized by the secondary development of

neurological symptoms in combination with blindness, known as Harding's disease. The pathology

is accompanied by foci of demyelination in the brain, which aggravates the clinical course.

Progressive vision loss is a reason for a comprehensive examination of the patient by an

ophthalmologist. Diagnostically important criteria: central scotoma, absence of pain syndrome,

the presence of similar symptoms in close relatives on the maternal line. The following tests are

used to confirm Leber's optic neuropathy:

Results:

Ophthalmoscopy. Fundus examination reveals swelling and waxy pallor of the

optic disc. Central disc excavation is within normal limits. In the early stages of the disease, retinal

hemorrhages are clearly visible during examination.

Visometry. It is impossible to assess visual acuity using standard tables, since this indicator

does not exceed 0.001. In practice, this corresponds to the ability to "count fingers near the face"

and distinguish silhouettes. In addition, perimetry is performed, which confirms the loss of central

visual fields.

Optical coherence tomography. Targeted examination of the macula of the retina shows

thinning and poor differentiation of all layers, flattening of the foveolar contour, and thickening of

the internal limiting membrane. OCT is the most informative method for diagnosing ON atrophy.

Visual acuity testing. Electrophysiological diagnostics of visual evoked potentials show a

decrease in nerve conduction in the preoptic area. The severity of these changes depends on the

degree of visual loss.

Molecular genetic testing. To confirm the diagnosis of Leber neuropathy, isolation of the

mitochondrial mutation is necessary. Patients are offered targeted testing for the 3 most common

point mutations and, if indicated, a multigene panel or complete mtDNA sequencing is performed.

In the acute stage, NONL should be differentiated from inflammatory diseases of the optic

nerve: retrobulbar neuritis, Devic optic myelitis, optic neuritis in rheumatic diseases. Ischemic


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optic neuropathy, which is characteristic of increased intraocular pressure, should be excluded.

The chronic stage of the disease is distinguished by compression of the optic nerve by tumors of

the orbit and chiasmatic-sellar region.

1.

Ophthalmological examination

2.

Ophthalmological examination

3.

Treatment of Leber's optic neuropathy

4.

Conservative therapy

Discussion:

For people with visual impairments, social and psychological adaptation is of

primary importance. The rehabilitation program consists of teaching independent movement,

spatial orientation, and self-care skills. All patients receive training in Braille, which allows them

to continue reading and studying. At the request of the person, labor rehabilitation and training in

skills (carving, music, sculpture) are carried out.

NONL with the 14484T>C mutation is considered prognostically favorable, with patients

having a chance of complete recovery of vision. The 3460G>A mutation has a very unfavorable

course and quickly leads to blindness. Anomaly 11778G<A has an intermediate prognosis. To

prevent the disease, patients with severe heredity are recommended to avoid provoking factors.

Conclusion:

In practical ophthalmology, there is no effective treatment regimen that would

improve the visual function of patients. Coenzyme Q10, levocarnitine, and cytochrome

preparations are prescribed as adjuvant and pathogenetic therapy. They are often combined into

"mitochondrial cocktails" to enhance their therapeutic effect. However, even long-term use of

drugs does not significantly affect clinical indicators.

Since drug therapy has not restored vision, scientists have placed great hopes in genetic

engineering technologies. Their essence is based on the transformation of mutant mitochondrial

DNA to a normal state in order to increase the ATP content in the axons of the visual pathway and

prevent nerve atrophy. Today, such methods are at the experimental stage, and some are

undergoing the first phase of clinical trials.

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гипертензия фонида тур пардв узгаришларида эндотелиал дисфункциянинг

маркерлари сифатида текшириш. Биомедицина ва амалиет журнали, 6(5), 203-210.

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Zhalalova, D. Z. (2022). The content of endothelin and homocysteine in blood and lacrimal

fluid in patients with hypertensive retinopathy Web of Scientist: International Scientific

Research Journal. ISSUE, 2, 958-963.

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Библиографические ссылки

БЕЛКА, F. S. Р. С. Р. (2022). В ПАТОГЕНЕЗЕ СОСУДИСТЫХ ЗАБОЛЕВАНИЙ ОРГАНА ЗРЕНИЯ У БОЛЬНЫХ АРТЕРИАЛЬНОЙ ГИПЕРТЕНЗИЕЙ.

Жалалова, Д. З., Кадирова, А. М., & Хамракулов, С. Б. (2021). Исходы герпетических кератоувеитов на фоне лечения препаратом «офтальмоферон» в зависимости от иммунного статуса пациентов. междисциплинарный подход по заболеваниям органов головы и шеи, 103.

ЖД, З., and А. БС. "РЕЗУЛЬТАТЫ ОЦЕНКИ УРОВНЯ ЭНДОТЕЛИНА-1 И Д-ДИМЕРОВ В СЛЕЗНОЙ ЖИДКОСТИ У ПАЦИЕНТОВ С АРТЕРИАЛЬНОЙ ГИПЕРТЕНЗИЕЙ." SCIENTIFIC JOURNAL OF APPLIED AND MEDICAL SCIENCES 3.3 (2024): 300-307.

Zhalalova, D. Z. OCT angiography in the assessment of retinal and choreoretinal microcirculation in patients with uncomplicated arterial hypertension International Ophthalmological Congress IOC Tashkent 2021.

Zhalalova, D. Z. Evaluation of markers of endothelial dysfunction in tear fluid in patients with arterial hypertension. Journal of Biomedicine in Amaliet. Tashkent-2022, Volume No., No. WITH.

Жалалова, Д. З. (2021). Эндотелин-1 ва гомоцистеин даражасини артериал гипертензия фонида тур пардв узгаришларида эндотелиал дисфункциянинг маркерлари сифатида текшириш. Биомедицина ва амалиет журнали, 6(5), 203-210.

Jalalova, D., Axmedov, A., Kuryazov, A., & Shernazarov, F. (2022). Combined dental and eye pathology. Science and innovation, 1(8), 91-100.

Zhalalova, D. Z. (2022). Pulatov US MICROCIRCULATORY DISORDERS IN THE VASCULAR SYSTEM OF THE BULBAR CONJUNCTIVA WITH INITIAL MANIFESTATIONS OF INSUFFICIENT BLOOD SUPPLY TO THE BRAIN. European journal of molecular medicine, 2(5).

Жалалова, Д. З. (2021). ОКТ-ангиография при оценке сосудистого русла сетчатки и хориоидеи. Биология ва тиббиет муаммолари, 6(130), 211-216.

Жалалова, Д. З. (2022). Классификационые критерии изменений сосудов сетчатки при артериальной гипертензии. In Международная научная конференция Университетская наука: взгляд в будущее (pp. 56-64).

Долиев, М. Н., Тулакова, Г. Э., Кадырова, А. М., Юсупов, З. А., & Жалалова, Д. З. (2016). Эффективность комбинированного лечения пациентов с центральной серозной хориоретинопатией. Вестник Башкирского государственного медицинского университета, (2), 64-66.

Жалалова, Д. З. Оценка маркеров эндотелиальной дисфункции в слезной жидкости у пациентов с артериальной гипертензиейЖурнал «Биомедицина ва амалиет». Тошкент-2022, Том №, №. С.

Жалалова, Д. З. (2021). ОКТ-ангиография в оценке ретинальной и хореоретинальной микроциркуляции у пациентов с неосложненой артериальной гипертензией/I Международный офтальмологческий конгресс IOC Uzbekistan, 2021 г. Ташкент, с, 96.

Shernazarov, F., Jalalova, D., Azimov, A., & CAUSES, S. A. (2022). SYMPTOMS, APPEARANCE, TREATMENT OF VARICOSE VEINS.

Жалалова, Д. З. (2021). Эндотелин-1 ва гомоцистеин даражасини артериал гипертензия фонида тур пардв узгаришларида эндотелиал дисфункциянинг маркерлари сифатида текшириш. Биомедицина ва амалиет журнали, 6(5), 203-210.

Shernazarov, F., Tohirova, J., & Jalalova, D. (2022). Types of hemorrhagic diseases, changes in newboens, their early diagnosis. Science and innovation, 1(D5), 16-22.

Zhalalova, D. Z. (2022). The content of endothelin and homocysteine in blood and lacrimal fluid in patients with hypertensive retinopathy Web of Scientist: International Scientific Research Journal. ISSUE, 2, 958-963.

Shernazarov, F., & Zuhridinovna, J. D. (2022). Microcirculation disorders in the vascular system of the bulbar conjunctiva in the initial manifestations of cerebral blood supply deficiency. Science and innovation, 1(Special Issue 2), 515-522.

Zhalalova, D. Z. (2022). Modern aspects of neuroprotektive treatment in hypertensive retinopathy Web of Scientist: International Scientific Research JournalVolume 3. ISSUE, 2, 949-952.

Жалалова, Д. З. (2009). Метод комбинированного лечения диабетической ретинопатии. Врач-аспирант, 37(10), 864-868.

Жалалова, Д. З. (2023). Результаты оценки эффективности комплексного лечения у пациентов с 3-4 стадиями гипертонической ангиоретинопатии. Miasto Przyszłości, 41, 33-36.

ЖД, З., & ИЖ, Ж. (2024). КЛАССИФИКАЦИЯ ГИПЕРТОНИЧЕСКОЙ РЕТИНОПАТИИ НА ОСНОВЕ ДАННЫХ ОПТИЧЕСКОЙ КОГЕРЕНТНОЙ ТОМОГРАФИИ. SCIENTIFIC JOURNAL OF APPLIED AND MEDICAL SCIENCES, 3(3), 336-342.

ЗЖД, Ж. (2024). КЛИНИКО-ФУНКЦИОНАЛЬНЫЕ ПОКАЗАТЕЛИ ОРГАНА ЗРЕНИЯ У ПАЦИЕНТОВ С ИШЕМИЧЕКИМИ ИЗМЕНЕНИЯМИ СОСУДОВ СЕТЧАТКИ. SCIENTIFIC JOURNAL OF APPLIED AND MEDICAL SCIENCES, 3(3), 286-293.

ЖД, З. (2024). ОЦЕНКА КЛИНИЧЕСКИХ И ФУНКЦИОНАЛЬНЫХ ПОКАЗАТЕЛЕЙ ЭНДОТЕЛИАЛЬНОЙ ДИСФУНКЦИИ В СЛЕЗНОЙ ЖИДКОСТИ У ПАЦИЕНТОВ С АРТЕРИАЛЬНОЙ ГИПЕРТЕНЗИЕЙ. SCIENTIFIC JOURNAL OF APPLIED AND MEDICAL SCIENCES, 3(3), 330-335.

Жалалова, Д. З. (2023). Актуальность проблемы изменений глазного дна при артериальной гипертензии. Miasto Przyszłości, 41, 37-40.